Bicornuate bicollis uterus is a congenital Mullerian anomaly which is comparatively rare. It is associated with about 25% of women having early miscarriage and infertility. The incidence of the bicornuate uterus along with vaginal anomalies is infrequent and unknown. We are presenting an unusual case of 25-year-old female with long-term primary infertility that was diagnosed with Bicornuate Bicollis uterus along with longitudinal vaginal septum. She underwent resection of vaginal septum and fallopian tubal recanalisation for tubal blockage, after which the patient conceived spontaneously and delivered a healthy male child later. Although these uterine anomalies are uncommon, they can still have profound medical and psychological implications.
Keywords: Bicornuate bicollis uterus, Vaginal septum, Infertility, Uterine anomaly